Somatic inactivation of Nf1 in hematopoietic cells results in a progressive myeloproliferative disorder.

نویسندگان

  • Doan T Le
  • Namie Kong
  • Yuan Zhu
  • Jennifer O Lauchle
  • Abigail Aiyigari
  • Benjamin S Braun
  • Endi Wang
  • Scott C Kogan
  • Michelle M Le Beau
  • Luis Parada
  • Kevin M Shannon
چکیده

The NF1 tumor suppressor gene encodes a guanosine triphosphotase (GTPase)-activating protein that negatively regulates Ras signaling and is inactivated in a subset of juvenile myelomonocytic leukemias (JMMLs). Adoptive transfer of fetal liver cells from Nf1 mutant mice models JMML; however, this system has important limitations as a platform for performing biologic and preclinical studies. We have exploited the interferon-inducible Mx1-Cre transgene to ablate a conditional mutant Nf1 allele in hematopoietic cells. Somatic inactivation of Nf1 induces a myeloproliferative disorder with 100% penetrance that is associated with a sub-acute clinical course, tissue infiltration by myeloid cells, hypersensitivity to granulocyte-macrophage colony stimulating factor, hyperproliferation, and resistance to apoptosis. These Mx1-Cre, Nf1(flox/flox) mice establish a tractable experimental model for testing therapeutics and for identifying mutations that cooperate with hyperactive Ras in myeloid leukemogenesis.

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عنوان ژورنال:
  • Blood

دوره 103 11  شماره 

صفحات  -

تاریخ انتشار 2004